PubMed:25905915
Annnotations
PubMed_ArguminSci
Id | Subject | Object | Predicate | Lexical cue |
---|---|---|---|---|
T1 | 128-230 | DRI_Approach | denotes | Cysteine string protein (CSPα) is a presynaptic J protein co-chaperone that opposes neurodegeneration. |
T2 | 231-330 | DRI_Background | denotes | Mutations in CSPα (i.e., Leu115 to Arg substitution or deletion (Δ) of Leu116) cause adult neuronal |
T3 | 353-410 | DRI_Background | denotes | (ANCL), a dominantly inherited neurodegenerative disease. |
T4 | 411-605 | DRI_Outcome | denotes | We have previously demonstrated that CSPα limits the expression of large conductance, calcium-activated K+ (BK) channels in neurons, which may impact synaptic excitability and neurotransmission. |
T5 | 606-773 | DRI_Outcome | denotes | Here we show by western blot analysis that expression of the pore-forming BKα subunit is elevated ~2.5 fold in the post-mortem cortex of a 36-year-old patient with the |
T6 | 787-796 | DRI_Outcome | denotes | mutation. |
T7 | 797-934 | DRI_Outcome | denotes | Moreover, we find that the increase in BKα subunit level is selective for ANCL and not a general feature of neurodegenerative conditions. |
T8 | 935-1128 | DRI_Background | denotes | While reduced levels of CSPα are found in some postmortem cortex specimens from Alzheimer's disease patients, we find no concomitant increase in BKα subunit expression in Alzheimer's specimens. |
T9 | 1129-1247 | DRI_Approach | denotes | Both CSPα monomer and oligomer expression are reduced in synaptosomes prepared from ANCL cortex compared with control. |
T10 | 1248-1314 | DRI_Background | denotes | In a cultured neuronal cell model, CSPα oligomers are short lived. |
T11 | 1315-1551 | DRI_Outcome | denotes | The results of this study indicate that the Leu116∆ mutation leads to elevated BKα subunit levels in human cortex and extend our initial work in rodent models demonstrating the modulation of BKα subunit levels by the same CSPα mutation. |
T12 | 1552-1731 | DRI_Challenge | denotes | While the precise sequence of pathogenic events still remains to be elucidated, our findings suggest that dysregulation of BK channels may contribute to neurodegeneration in ANCL. |
PubmedHPO
Id | Subject | Object | Predicate | Lexical cue |
---|---|---|---|---|
T1 | 212-229 | HP_0002180 | denotes | neurodegeneration |
T2 | 1015-1034 | HP_0002511 | denotes | Alzheimer's disease |
T3 | 1705-1722 | HP_0002180 | denotes | neurodegeneration |
DisGeNET5_variant_disease
Id | Subject | Object | Predicate | Lexical cue |
---|---|---|---|---|
25905915-2#25#38#geners387907043 | 256-269 | geners387907043 | denotes | Leu115 to Arg |
25905915-2#85#121#diseaseC0022797 | 316-352 | diseaseC0022797 | denotes | adult neuronal ceroid lipofuscinosis |
25905915-2#123#127#diseaseC0022797 | 354-358 | diseaseC0022797 | denotes | ANCL |
25905915-2#153#178#diseaseC0524851 | 384-409 | diseaseC0524851 | denotes | neurodegenerative disease |
25#38#geners38790704385#121#diseaseC0022797 | 25905915-2#25#38#geners387907043 | 25905915-2#85#121#diseaseC0022797 | associated_with | Leu115 to Arg,adult neuronal ceroid lipofuscinosis |
25#38#geners387907043123#127#diseaseC0022797 | 25905915-2#25#38#geners387907043 | 25905915-2#123#127#diseaseC0022797 | associated_with | Leu115 to Arg,ANCL |
25#38#geners387907043153#178#diseaseC0524851 | 25905915-2#25#38#geners387907043 | 25905915-2#153#178#diseaseC0524851 | associated_with | Leu115 to Arg,neurodegenerative disease |
DisGeNET5_gene_disease
Id | Subject | Object | Predicate | Lexical cue |
---|---|---|---|---|
25905915-0#69#80#gene3778 | 69-80 | gene3778 | denotes | BK) Channel |
25905915-0#96#126#diseaseC0027877 | 96-126 | diseaseC0027877 | denotes | Neuronal Ceroid Lipofuscinosis |
25905915-2#13#17#gene80331 | 244-248 | gene80331 | denotes | CSPα |
25905915-2#153#178#diseaseC0524851 | 384-409 | diseaseC0524851 | denotes | neurodegenerative disease |
25905915-6#24#28#gene80331 | 959-963 | gene80331 | denotes | CSPα |
25905915-6#80#99#diseaseC0002395 | 1015-1034 | diseaseC0002395 | denotes | Alzheimer's disease |
25905915-7#5#9#gene80331 | 1134-1138 | gene80331 | denotes | CSPα |
25905915-7#84#88#diseaseC0022797 | 1213-1217 | diseaseC0022797 | denotes | ANCL |
69#80#gene377896#126#diseaseC0027877 | 25905915-0#69#80#gene3778 | 25905915-0#96#126#diseaseC0027877 | associated_with | BK) Channel,Neuronal Ceroid Lipofuscinosis |
13#17#gene80331153#178#diseaseC0524851 | 25905915-2#13#17#gene80331 | 25905915-2#153#178#diseaseC0524851 | associated_with | CSPα,neurodegenerative disease |
24#28#gene8033180#99#diseaseC0002395 | 25905915-6#24#28#gene80331 | 25905915-6#80#99#diseaseC0002395 | associated_with | CSPα,Alzheimer's disease |
5#9#gene8033184#88#diseaseC0022797 | 25905915-7#5#9#gene80331 | 25905915-7#84#88#diseaseC0022797 | associated_with | CSPα,ANCL |