| Id |
Subject |
Object |
Predicate |
Lexical cue |
| TextSentencer_T1 |
0-88 |
Sentence |
denotes |
Neurological features of epilepsy, ataxia, sensorineural deafness, tubulopathy syndrome. |
| TextSentencer_T2 |
89-93 |
Sentence |
denotes |
AIM: |
| TextSentencer_T3 |
94-304 |
Sentence |
denotes |
Recently, we reported a previously unrecognized symptom constellation comprising epilepsy, ataxia, sensorineural deafness, and tubulopathy (EAST syndrome) associated with recessive mutations in the KCNJ10 gene. |
| TextSentencer_T4 |
305-516 |
Sentence |
denotes |
Here, we provide a detailed characterization of the clinical features of the syndrome to aid patient management with respect to diagnosis, prognostic counselling, and identification of best treatment modalities. |
| TextSentencer_T5 |
517-524 |
Sentence |
denotes |
METHOD: |
| TextSentencer_T6 |
525-740 |
Sentence |
denotes |
We conducted a retrospective review of the detailed neurological and neuroradiological features of nine children (four females, five males; age range at last examination 6-20y) with genetically proven EAST syndrome. |
| TextSentencer_T7 |
741-749 |
Sentence |
denotes |
RESULTS: |
| TextSentencer_T8 |
750-811 |
Sentence |
denotes |
All children presented with tonic-clonic seizures in infancy. |
| TextSentencer_T9 |
812-882 |
Sentence |
denotes |
Later, non-progressive, cerebellar ataxia and hearing loss were noted. |
| TextSentencer_T10 |
883-1019 |
Sentence |
denotes |
Whilst seizures mostly responded well to treatment, ataxia proved to be the most debilitating feature, with three patients non-ambulant. |
| TextSentencer_T11 |
1020-1143 |
Sentence |
denotes |
All available magnetic resonance imaging (MRI) revealed subtle symmetrical signal changes in the cerebellar dentate nuclei. |
| TextSentencer_T12 |
1144-1256 |
Sentence |
denotes |
Moreover, four patients had a small corpus callosum and brainstem hypoplasia, and three had a small spinal cord. |
| TextSentencer_T13 |
1257-1423 |
Sentence |
denotes |
Regional quantitative volumetric analysis of the images confirmed the corpus callosum and brainstem hypoplasia and showed further patterns of variation from the norm. |
| TextSentencer_T14 |
1424-1439 |
Sentence |
denotes |
INTERPRETATION: |
| TextSentencer_T15 |
1440-1559 |
Sentence |
denotes |
The neurological features of EAST syndrome appear to be non-progressive, which is important for prognostic counselling. |
| TextSentencer_T16 |
1560-1662 |
Sentence |
denotes |
The spectrum of EAST syndrome includes consistent abnormalities on brain MRI, which may aid diagnosis. |
| TextSentencer_T17 |
1663-1764 |
Sentence |
denotes |
Further longitudinal documentation is required to determine the true natural history of the disorder. |
| T1 |
0-88 |
Sentence |
denotes |
Neurological features of epilepsy, ataxia, sensorineural deafness, tubulopathy syndrome. |
| T2 |
89-93 |
Sentence |
denotes |
AIM: |
| T3 |
94-304 |
Sentence |
denotes |
Recently, we reported a previously unrecognized symptom constellation comprising epilepsy, ataxia, sensorineural deafness, and tubulopathy (EAST syndrome) associated with recessive mutations in the KCNJ10 gene. |
| T4 |
305-516 |
Sentence |
denotes |
Here, we provide a detailed characterization of the clinical features of the syndrome to aid patient management with respect to diagnosis, prognostic counselling, and identification of best treatment modalities. |
| T5 |
517-524 |
Sentence |
denotes |
METHOD: |
| T6 |
525-740 |
Sentence |
denotes |
We conducted a retrospective review of the detailed neurological and neuroradiological features of nine children (four females, five males; age range at last examination 6-20y) with genetically proven EAST syndrome. |
| T7 |
741-749 |
Sentence |
denotes |
RESULTS: |
| T8 |
750-811 |
Sentence |
denotes |
All children presented with tonic-clonic seizures in infancy. |
| T9 |
812-882 |
Sentence |
denotes |
Later, non-progressive, cerebellar ataxia and hearing loss were noted. |
| T10 |
883-1019 |
Sentence |
denotes |
Whilst seizures mostly responded well to treatment, ataxia proved to be the most debilitating feature, with three patients non-ambulant. |
| T11 |
1020-1143 |
Sentence |
denotes |
All available magnetic resonance imaging (MRI) revealed subtle symmetrical signal changes in the cerebellar dentate nuclei. |
| T12 |
1144-1256 |
Sentence |
denotes |
Moreover, four patients had a small corpus callosum and brainstem hypoplasia, and three had a small spinal cord. |
| T13 |
1257-1423 |
Sentence |
denotes |
Regional quantitative volumetric analysis of the images confirmed the corpus callosum and brainstem hypoplasia and showed further patterns of variation from the norm. |
| T14 |
1424-1439 |
Sentence |
denotes |
INTERPRETATION: |
| T15 |
1440-1559 |
Sentence |
denotes |
The neurological features of EAST syndrome appear to be non-progressive, which is important for prognostic counselling. |
| T16 |
1560-1662 |
Sentence |
denotes |
The spectrum of EAST syndrome includes consistent abnormalities on brain MRI, which may aid diagnosis. |
| T17 |
1663-1764 |
Sentence |
denotes |
Further longitudinal documentation is required to determine the true natural history of the disorder. |