PubMed:20410308
Annnotations
sentences
| Id | Subject | Object | Predicate | Lexical cue |
|---|---|---|---|---|
| T1 | 0-149 | Sentence | denotes | Y65C missense mutation in the WW domain of the Golabi-Ito-Hall syndrome protein PQBP1 affects its binding activity and deregulates pre-mRNA splicing. |
| T2 | 150-282 | Sentence | denotes | The PQBP1 (polyglutamine tract-binding protein 1) gene encodes a nuclear protein that regulates pre-mRNA splicing and transcription. |
| T3 | 283-420 | Sentence | denotes | Mutations in the PQBP1 gene were reported in several X chromosome-linked mental retardation disorders including Golabi-Ito-Hall syndrome. |
| T4 | 421-600 | Sentence | denotes | The missense mutation that causes this syndrome is unique among other PQBP1 mutations reported to date because it maps within a functional domain of PQBP1, known as the WW domain. |
| T5 | 601-731 | Sentence | denotes | The mutation substitutes tyrosine 65 with cysteine and is located within the conserved core of aromatic amino acids of the domain. |
| T6 | 732-891 | Sentence | denotes | We show here that the binding property of the Y65C-mutated WW domain and the full-length mutant protein toward its cognate proline-rich ligands was diminished. |
| T7 | 892-1064 | Sentence | denotes | Furthermore, in Golabi-Ito-Hall-derived lymphoblasts we showed that the complex between PQBP1-Y65C and WBP11 (WW domain-binding protein 11) splicing factor was compromised. |
| T8 | 1065-1148 | Sentence | denotes | In these cells a substantial decrease in pre-mRNA splicing efficiency was detected. |
| T9 | 1149-1404 | Sentence | denotes | Our study points to the critical role of the WW domain in the function of the PQBP1 protein and provides an insight into the molecular mechanism that underlies the X chromosome-linked mental retardation entities classified globally as Renpenning syndrome. |
DisGeNET
| Id | Subject | Object | Predicate | Lexical cue |
|---|---|---|---|---|
| T0 | 80-85 | gene:10084 | denotes | PQBP1 |
| T1 | 47-71 | disease:C0796135 | denotes | Golabi-Ito-Hall syndrome |
| T2 | 300-305 | gene:10084 | denotes | PQBP1 |
| T3 | 395-419 | disease:C0796135 | denotes | Golabi-Ito-Hall syndrome |
| R1 | T0 | T1 | associated_with | PQBP1,Golabi-Ito-Hall syndrome |
| R2 | T2 | T3 | associated_with | PQBP1,Golabi-Ito-Hall syndrome |
PubmedHPO
| Id | Subject | Object | Predicate | Lexical cue |
|---|---|---|---|---|
| T1 | 356-374 | HP_0001249 | denotes | mental retardation |
| T2 | 1333-1351 | HP_0001249 | denotes | mental retardation |
DisGeNET5_variant_disease
| Id | Subject | Object | Predicate | Lexical cue |
|---|---|---|---|---|
| 20410308-0#0#4#geners121917899 | 0-4 | geners121917899 | denotes | Y65C |
| 20410308-0#47#71#diseaseC0796135 | 47-71 | diseaseC0796135 | denotes | Golabi-Ito-Hall syndrome |
| 0#4#geners12191789947#71#diseaseC0796135 | 20410308-0#0#4#geners121917899 | 20410308-0#47#71#diseaseC0796135 | associated_with | Y65C,Golabi-Ito-Hall syndrome |
DisGeNET5_gene_disease
| Id | Subject | Object | Predicate | Lexical cue |
|---|---|---|---|---|
| 20410308-0#80#85#gene10084 | 80-85 | gene10084 | denotes | PQBP1 |
| 20410308-0#47#71#diseaseC0796135 | 47-71 | diseaseC0796135 | denotes | Golabi-Ito-Hall syndrome |
| 20410308-8#78#83#gene10084 | 1227-1232 | gene10084 | denotes | PQBP1 |
| 20410308-8#184#202#diseaseC0025362 | 1333-1351 | diseaseC0025362 | denotes | mental retardation |
| 20410308-8#184#202#diseaseC3714756 | 1333-1351 | diseaseC3714756 | denotes | mental retardation |
| 80#85#gene1008447#71#diseaseC0796135 | 20410308-0#80#85#gene10084 | 20410308-0#47#71#diseaseC0796135 | associated_with | PQBP1,Golabi-Ito-Hall syndrome |
| 78#83#gene10084184#202#diseaseC0025362 | 20410308-8#78#83#gene10084 | 20410308-8#184#202#diseaseC0025362 | associated_with | PQBP1,mental retardation |
| 78#83#gene10084184#202#diseaseC3714756 | 20410308-8#78#83#gene10084 | 20410308-8#184#202#diseaseC3714756 | associated_with | PQBP1,mental retardation |
mondo_disease
| Id | Subject | Object | Predicate | Lexical cue | mondo_id |
|---|---|---|---|---|---|
| T1 | 47-71 | Disease | denotes | Golabi-Ito-Hall syndrome | http://purl.obolibrary.org/obo/MONDO_0010653 |
| T2 | 356-374 | Disease | denotes | mental retardation | http://purl.obolibrary.org/obo/MONDO_0001071 |
| T3 | 395-419 | Disease | denotes | Golabi-Ito-Hall syndrome | http://purl.obolibrary.org/obo/MONDO_0010653 |
| T4 | 1333-1351 | Disease | denotes | mental retardation | http://purl.obolibrary.org/obo/MONDO_0001071 |
| T5 | 1384-1403 | Disease | denotes | Renpenning syndrome | http://purl.obolibrary.org/obo/MONDO_0010653 |
Anatomy-UBERON
| Id | Subject | Object | Predicate | Lexical cue | uberon_id |
|---|---|---|---|---|---|
| T1 | 175-180 | Body_part | denotes | tract | http://purl.obolibrary.org/obo/UBERON_0001018 |
| T2 | 338-348 | Body_part | denotes | chromosome | http://purl.obolibrary.org/obo/GO_0005694 |
| T3 | 1315-1325 | Body_part | denotes | chromosome | http://purl.obolibrary.org/obo/GO_0005694 |
HP-phenotype
| Id | Subject | Object | Predicate | Lexical cue | hp_id |
|---|---|---|---|---|---|
| T1 | 356-374 | Phenotype | denotes | mental retardation | HP:0001249 |
| T2 | 1333-1351 | Phenotype | denotes | mental retardation | HP:0001249 |
CL-cell
| Id | Subject | Object | Predicate | Lexical cue | cl_id |
|---|---|---|---|---|---|
| T1 | 932-944 | Cell | denotes | lymphoblasts | http://purl.obolibrary.org/obo/CL:0017005 |